IDEAS home Printed from https://ideas.repec.org/a/gam/jijerp/v20y2023i3p2483-d1051758.html
   My bibliography  Save this article

Literature Review on Health Emigration in Rare Diseases—A Machine Learning Perspective

Author

Listed:
  • Małgorzata Skweres-Kuchta

    (Department of Organization and Management, Institute of Management, University of Szczecin, Cukrowa 8 Street, 71-004 Szczecin, Poland)

  • Iwona Czerska

    (Department of Marketing Research, Faculty of Management, Wroclaw University of Economics and Business, 118/120 Komandorska Str, 53-345 Wroclaw, Poland)

  • Elżbieta Szaruga

    (Department of Transport Management, Institute of Management, University of Szczecin, Cukrowa 8 Street, 71-004 Szczecin, Poland)

Abstract

The article deals with one of the effects of health inequalities and gaps in access to treatments for rare diseases, namely health-driven emigration. The purpose of the paper is to systematize knowledge about the phenomenon of health emigration observed among families affected by rare diseases, for which reimbursed treatment is available, but only in selected countries. The topic proved to be niche; the issue of “health emigration in rare diseases” is an area for exploration. Therefore, the further analysis used text mining and machine learning methods based on a database selected based on keywords related to this issue. The results made it possible to systematize the guesses made by researchers in management and economic fields, to identify the most common keywords and thematic clusters around the perspective of the patient, drug manufacturer and treatment reimbursement decision-maker, and the perspective integrating all the others. Since the topic of health emigration was not directly addressed in the selected sources, the authors attempted to define the related concepts and discussed the importance of this phenomenon in managing the support system in rare diseases. Thus, they indicated directions for further research in this area.

Suggested Citation

  • Małgorzata Skweres-Kuchta & Iwona Czerska & Elżbieta Szaruga, 2023. "Literature Review on Health Emigration in Rare Diseases—A Machine Learning Perspective," IJERPH, MDPI, vol. 20(3), pages 1-31, January.
  • Handle: RePEc:gam:jijerp:v:20:y:2023:i:3:p:2483-:d:1051758
    as

    Download full text from publisher

    File URL: https://www.mdpi.com/1660-4601/20/3/2483/pdf
    Download Restriction: no

    File URL: https://www.mdpi.com/1660-4601/20/3/2483/
    Download Restriction: no
    ---><---

    References listed on IDEAS

    as
    1. Kessel, Maura & Hannemann-Weber, Henrike & Kratzer, Jan, 2012. "Innovative work behavior in healthcare: The benefit of operational guidelines in the treatment of rare diseases," Health Policy, Elsevier, vol. 105(2), pages 146-153.
    2. Nicole B. Simpson, 2022. "Demographic and economic determinants of migration," IZA World of Labor, Institute of Labor Economics (IZA), pages 373-373, July.
    3. Patrizio Armeni & Marianna Cavazza & Entela Xoxi & Domenica Taruscio & Yllka Kodra, 2021. "Reflections on the Importance of Cost of Illness Analysis in Rare Diseases: A Proposal," IJERPH, MDPI, vol. 18(3), pages 1-18, January.
    4. Michael Drummond & Adrian Towse, 2014. "Orphan drugs policies: a suitable case for treatment," The European Journal of Health Economics, Springer;Deutsche Gesellschaft für Gesundheitsökonomie (DGGÖ), vol. 15(4), pages 335-340, May.
    5. Belousova, Olga A. & Groen, Aard J. & Ouendag, Aniek M., 2020. "Opportunities and barriers for innovation and entrepreneurship in orphan drug development," Technological Forecasting and Social Change, Elsevier, vol. 161(C).
    6. Gregory S. Zaric, 2008. "Optimal drug pricing, limited use conditions and stratified net benefits for Markov models of disease progression," Health Economics, John Wiley & Sons, Ltd., vol. 17(11), pages 1277-1294, November.
    7. Lundberg, Ian & Brand, Jennie E. & Jeon, Nanum, 2022. "Researcher reasoning meets computational capacity: Machine learning for social science," SocArXiv s5zc8, Center for Open Science.
    8. Javier Orofino & Javier Soto & Miguel Casado & Itziar Oyagüez, 2010. "Global spending on orphan drugs in France, Germany, the UK, Italy and Spain during 2007," Applied Health Economics and Health Policy, Springer, vol. 8(5), pages 301-315, September.
    9. Gregory S. Zaric, 2008. "Optimal drug pricing, limited use conditions and stratified net benefits for Markov models of disease progression," Health Economics, John Wiley & Sons, Ltd., vol. 17(11), pages 1277-1294.
    10. Elżbieta Szaruga & Elżbieta Załoga, 2022. "Qualitative–Quantitative Warning Modeling of Energy Consumption Processes in Inland Waterway Freight Transport on River Sections for Environmental Management," Energies, MDPI, vol. 15(13), pages 1-21, June.
    11. Jonathan Cortés-Martín & Lourdes Díaz-Rodríguez & Beatriz Piqueras-Sola & Raquel Rodríguez-Blanque & Antonio Bermejo-Fernández & Juan Carlos Sánchez-García, 2020. "Hajdu–Cheney Syndrome: A Systematic Review of the Literature," IJERPH, MDPI, vol. 17(17), pages 1-18, August.
    12. Linda Yamoah & Nick Dragojlovic & Alesha Smith & Larry D. Lynd & Carlo A. Marra, 2021. "Evaluating New Zealanders’ Values for Drug Coverage Decision Making: Trade-Offs between Treatments for Rare and Common Conditions," PharmacoEconomics, Springer, vol. 39(1), pages 109-119, January.
    Full references (including those not matched with items on IDEAS)

    Most related items

    These are the items that most often cite the same works as this one and are cited by the same works as this one.
    1. Reza Mahjoub & Fredrik Ødegaard & Gregory S. Zaric, 2018. "Evaluation of a pharmaceutical risk‐sharing agreement when patients are screened for the probability of success," Health Economics, John Wiley & Sons, Ltd., vol. 27(1), pages 15-25, January.
    2. Alan J. Girling & Richard J. Lilford & Terry P. Young, 2012. "Pricing Of Medical Devices Under Coverage Uncertainty—A Modelling Approach," Health Economics, John Wiley & Sons, Ltd., vol. 21(12), pages 1502-1507, December.
    3. Puig-Junoy, Jaume & López-Valcárcel, Beatriz González, 2014. "Launch prices for new pharmaceuticals in the heavily regulated and subsidized Spanish market, 1995–2007," Health Policy, Elsevier, vol. 116(2), pages 170-181.
    4. Degtiar, Irina, 2017. "A review of international coverage and pricing strategies for personalized medicine and orphan drugs," Health Policy, Elsevier, vol. 121(12), pages 1240-1248.
    5. Jeremy D. Goldhaber-Fiebert & Lauren E. Cipriano, 2023. "Pricing Treatments Cost-Effectively when They Have Multiple Indications: Not Just a Simple Threshold Analysis," Medical Decision Making, , vol. 43(7-8), pages 914-929, October.
    6. Serdar Öztürk & Buket Altınöz, 2022. "An Investigation of the Impact of Health Expenditures on International Migration as a Pull Factor in OECD Countries Using a Panel Vector Autoregression (PVAR) Approach," Journal of Economic Policy Researches, Istanbul University, Faculty of Economics, vol. 9(1), pages 39-52, January.
    7. Inese Mavlutova & Dzintra Atstaja & Janis Grasis & Jekaterina Kuzmina & Inga Uvarova & Dagnija Roga, 2023. "Urban Transportation Concept and Sustainable Urban Mobility in Smart Cities: A Review," Energies, MDPI, vol. 16(8), pages 1-16, April.
    8. Nicod, Elena & Annemans, Lieven & Bucsics, Anna & Lee, Anne & Upadhyaya, Sheela & Facey, Karen, 2019. "HTA programme response to the challenges of dealing with orphan medicinal products: Process evaluation in selected European countries," Health Policy, Elsevier, vol. 123(2), pages 140-151.
    9. Witsarut Achariyaviriya & Wongkot Wongsapai & Kittitat Janpoom & Tossapon Katongtung & Yuttana Mona & Nakorn Tippayawong & Pana Suttakul, 2023. "Estimating Energy Consumption of Battery Electric Vehicles Using Vehicle Sensor Data and Machine Learning Approaches," Energies, MDPI, vol. 16(17), pages 1-14, September.
    10. Oudom Hean, 2022. "The Effects of Technological Progress in Innovative Regions on the Labor Markets of Lagging Regions: A Theoretical Perspective," Economies, MDPI, vol. 10(8), pages 1-12, August.
    11. Elżbieta Szaruga & Bartosz Pilecki & Marta Sidorkiewicz, 2023. "The Impact of the COVID-19 Pandemic, Transport Accessibility, and Accommodation Accessibility on the Energy Intensity of Public Tourist Transport," Energies, MDPI, vol. 16(19), pages 1-27, October.
    12. Veronika Kalouguina & Joël Wagner, 2020. "Challenges and Solutions for Integrating and Financing Personalized Medicine in Healthcare Systems: A Systematic Literature Review," JRFM, MDPI, vol. 13(11), pages 1-22, November.
    13. Michael Drummond & Aleksandra Torbica & Rosanna Tarricone, 2020. "Should health technology assessment be more patient centric? If so, how?," The European Journal of Health Economics, Springer;Deutsche Gesellschaft für Gesundheitsökonomie (DGGÖ), vol. 21(8), pages 1117-1120, November.
    14. Moors, Ellen H.M. & Kukk Fischer, Piret & Boon, Wouter P.C. & Schellen, Frank & Negro, Simona O., 2018. "Institutionalisation of markets: The case of personalised cancer medicine in the Netherlands," Technological Forecasting and Social Change, Elsevier, vol. 128(C), pages 133-143.
    15. Amr Abdelwahed & Anne Goujon & Leiwen Jiang, 2020. "The Migration Intentions of Young Egyptians," Sustainability, MDPI, vol. 12(23), pages 1-38, November.
    16. Serina Chang & Adam Fourney & Eric Horvitz, 2024. "Measuring vaccination coverage and concerns of vaccine holdouts from web search logs," Nature Communications, Nature, vol. 15(1), pages 1-21, December.
    17. Letycja Sołoducho-Pelc & Adam Sulich, 2022. "Natural Environment Protection Strategies and Green Management Style: Literature Review," Sustainability, MDPI, vol. 14(17), pages 1-25, August.
    18. Rodica Pripoaie & Carmen-Mihaela Cretu & Anca-Gabriela Turtureanu & Carmen-Gabriela Sirbu & Emanuel Ştefan Marinescu & Laurentiu-Gabriel Talaghir & Florentina Chițu & Daniela Monica Robu, 2022. "A Statistical Analysis of the Migration Process: A Case Study—Romania," Sustainability, MDPI, vol. 14(5), pages 1-27, February.
    19. Paulo Reis Mourao, 2021. "Footsteps in the sand: studying refugee paths since 2005 through a network analysis of 205 territories," Quality & Quantity: International Journal of Methodology, Springer, vol. 55(2), pages 563-600, April.
    20. Monika Wagner & Hanane Khoury & Jacob Willet & Donna Rindress & Mireille Goetghebeur, 2016. "Can the EVIDEM Framework Tackle Issues Raised by Evaluating Treatments for Rare Diseases: Analysis of Issues and Policies, and Context-Specific Adaptation," PharmacoEconomics, Springer, vol. 34(3), pages 285-301, March.

    Corrections

    All material on this site has been provided by the respective publishers and authors. You can help correct errors and omissions. When requesting a correction, please mention this item's handle: RePEc:gam:jijerp:v:20:y:2023:i:3:p:2483-:d:1051758. See general information about how to correct material in RePEc.

    If you have authored this item and are not yet registered with RePEc, we encourage you to do it here. This allows to link your profile to this item. It also allows you to accept potential citations to this item that we are uncertain about.

    If CitEc recognized a bibliographic reference but did not link an item in RePEc to it, you can help with this form .

    If you know of missing items citing this one, you can help us creating those links by adding the relevant references in the same way as above, for each refering item. If you are a registered author of this item, you may also want to check the "citations" tab in your RePEc Author Service profile, as there may be some citations waiting for confirmation.

    For technical questions regarding this item, or to correct its authors, title, abstract, bibliographic or download information, contact: MDPI Indexing Manager (email available below). General contact details of provider: https://www.mdpi.com .

    Please note that corrections may take a couple of weeks to filter through the various RePEc services.

    IDEAS is a RePEc service. RePEc uses bibliographic data supplied by the respective publishers.